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Nystagmus 7, Congenital, AD

OMIM ID:

autosomal dominant

Nystagmus 7, Congenital, AD

Alternate Names

NYS7

Defective Genes

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Clinical Characteristics

Ocular Features

A pendular nystagmus is usually diagnosed in infancy.  The eye is otherwise anatomically and functionally normal.  No photophobia, hypopigmentation, night blindness have been noted in the two Chinese families reported.  The ERG and foveal appearance are normal.  Visual acuity has not been reported.

Systemic Features

No systemic abnormalities have been found.

Genetics

Inheritance

The two reported multigenerational pedigrees show a pattern consistent with autosomal dominant inheritance. No causative mutation has been identified but mapping suggests a locus at 1q31-q32.2 that segregates with the condition.

Nystagmus 2 (164100), nystagmus 3 (608345), and nystagmus 4 (614826) are other autosomal dominant forms of simple nystagmus but they are unique disorders as they map to other chromosomal locations.

Several forms of X-linked recessive inheritance are contained in this database: NYS1, NYS5, and NYS6.

Pedigree

Autosomal dominant

Autosomal dominant disorders require only one mutation for the disease to be expressed.  Since an affected parent has two chromosomes, only one of which has the mutant gene, parents can expect that half (50%) of their children will receive that one and inherit the disease.  It is common for individuals that inherit the mutation, however, to not have evidence of the disease (nonpenetrance).

Image
Sample pedigree of autosomal dominant inheritance

Autosomal dominant inheritance leads to a vertical pattern of transmission

Treatment & Management

No treatment has been reported. 

Selected Resources

Web Resources

Publications

Displaying 1 - 2 of 2

A novel locus for autosomal dominant congenital motor nystagmus mapped to 1q31-q32.2 between D1S2816 and D1S2692

PubMedID: 22065086

Confirmation and refinement of an autosomal dominant congenital motor nystagmus locus in chromosome 1q31.3–q32.1

PubMedID: 22914672