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Mental Retardation, AD 53

OMIM ID:

autosomal dominant

Mental Retardation, AD 53

Alternate Names

MRD53

Defective Genes

CAMK2A

Clinical Characteristics

Ocular Features

Dysmorphism of periocular structures includes downward slanting lid fissures, hypertelorism, and epicanthal folds.  Evidence for visual problems comes from visual tracking difficulties in some individuals.  Strabismus is present in a minority of patients.

Systemic Features

Delayed global development, cognitive impairment, and intellectual disability are major features of this form of mental retardation.  Hypotonia is present early.  Severe delays in onset of speech and walking are found in all patients and never develop in many individuals.  Behavior problems include, anxiety, hyperactivity, aggression, and autistic traits.  Feeding problems and breathing irregularities have been reported.  Seizures occur in some patients.

Brain MRIs are generally normal although corpus callosum anomalies are sometimes identified.

Genetics

Inheritance

Heterozygous mutations in the CAMK2A gene (5q32) have been found in individuals with this disorder.

Pedigree

Autosomal dominant

Autosomal dominant disorders require only one mutation for the disease to be expressed.  Since an affected parent has two chromosomes, only one of which has the mutant gene, parents can expect that half (50%) of their children will receive that one and inherit the disease.  It is common for individuals that inherit the mutation, however, to not have evidence of the disease (nonpenetrance).

Image
Sample pedigree of autosomal dominant inheritance

Autosomal dominant inheritance leads to a vertical pattern of transmission

Treatment & Management

No treatment for the general condition has been reported.

Selected Resources

Web Resources

Publications

Displaying 1 - 1 of 1

De Novo Mutations in Protein Kinase Genes CAMK2A and CAMK2B Cause Intellectual Disability

PubMedID: 29100089