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Cataracts, Congenital Nuclear

OMIM ID:

autosomal recessive

Cataracts, Congenital Nuclear

Alternate Names

CATCN1
CATCN2
CATCN3

Defective Genes

CRYBB1
CRYBB3

Clinical Characteristics

Ocular Features

Congenital nuclear cataracts are the only ocular abnormalities in these conditions.  There may be some cortical opacifications as well.  The nuclear opacifications may not be sufficiently dense in some patients to require cataract surgery.  Nothing is known of their natural history, however.

Systemic Features

No systemic disease is associated with these congenital cataracts.

Genetics

Inheritance

All three of these nuclear cataracts are inherited in autosomal recessive patterns.  They have been reported in rare families in which the parents were consanguineous.

CATCN1 was reported in a 4-generation Pakistani family having an unknown mutation localized to 19q13.

Another congenital nuclear cataract (CATCN2) results from mutations in the CRYBB3 (22q11.23) gene reported in 2 consanguineous Pakistani families.

CATCN3 results from mutations in CRYBB1 (22q12.1) as reported in two consanguineous Israeli Bedouin families with 14 affected individuals.

Pedigree

Autosomal recessive

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent.  Carriers with only one mutation, such as the parents, do not have clinical disease.  Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Image
Sample pedigree of autosomal recessive inheritance

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent. Carriers with only one mutation, such as the parents, do not have clinical disease. Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Treatment & Management

Surgical removal may be indicated if the lens opacities are visually significant.  Vision may be sufficiently impaired in some children that surgery is required before 2 years of age.

Selected Resources

Web Resources

Publications

Displaying 1 - 3 of 3

A New Locus for Autosomal Recessive Nuclear Cataract Mapped to Chromosome 19q13 in a Pakistani Family

PubMedID: 15671291

HomozygousCRYBB1Deletion Mutation Underlies Autosomal Recessive Congenital Cataract

PubMedID: 17460281

Mutations in βB3-Crystallin Associated with Autosomal Recessive Cataract in Two Pakistani Families

PubMedID: 15914629