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Cataracts, Congenital, Autosomal Recessive 5

OMIM ID:

autosomal recessive

Cataracts, Congenital, Autosomal Recessive 5

Alternate Names

CATC5

Defective Genes

AGK

Clinical Characteristics

Ocular Features

This type of autosomal recessive congenital cataract has been identified in a single consanguineous family.  The lens opacities (not further characterized) are the only ocular abnormalities found in two boys and 1 girl belonging to a single sibship born to parent who were second cousins.  Extensive systemic evaluations found no evidence of clinical disease as found in Sengers syndrome (212350).

Systemic Features

There are no systemic abnormalities.

Genetics

Inheritance

This type of cataract results from homozygous mutations in AGK (7q33-q36.1), a lipid metabolism gene.  Sengers syndrome (212350) is also caused by mutations in the same gene.

Pedigree

Autosomal recessive

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent.  Carriers with only one mutation, such as the parents, do not have clinical disease.  Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Image
Sample pedigree of autosomal recessive inheritance

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent. Carriers with only one mutation, such as the parents, do not have clinical disease. Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Treatment & Management

Cataract surgery may be indicated if the opacities are visually significant..

Selected Resources

Web Resources

Publications

Displaying 1 - 1 of 1

Identification of a truncation mutation of acylglycerol kinase (AGK) gene in a novel autosomal recessive cataract locus

PubMedID: 22415731