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Cataracts, Congenital, Autosomal Recessive 2

OMIM ID:

autosomal recessive

Cataracts, Congenital, Autosomal Recessive 2

Alternate Names

CATC2

Defective Genes

FYCO1

Clinical Characteristics

Ocular Features

Bilateral nuclear lens opacities are either present at birth or noted during infancy.  The cataracts were sufficiently dense that surgery is necessary within several months of age in most patients.  No other ocular disease is present.

Systemic Features

No systemic abnormalities are present.

Genetics

Inheritance

CATC2 is an autosomal recessive condition that has been reported in 12 consanguineous Pakistani families.  Homozygous mutations in FYCO1 (3p21.31) segregated with the lens opacities as expected.  Mutations in FYC01 are among the most common causes of congenital cataracts in Pakistan and may account for about 10% of the total genetic load of cataracts in this country.  Mutations in the same gene have been found segregating in several consanguineous Arab families with congenital cataracts as well.

Pedigree

Autosomal recessive

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent.  Carriers with only one mutation, such as the parents, do not have clinical disease.  Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Image
Sample pedigree of autosomal recessive inheritance

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent. Carriers with only one mutation, such as the parents, do not have clinical disease. Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Treatment & Management

Cataract surgery is frequently necessary during infancy.

Publications

Displaying 1 - 2 of 2

A gene causing autosomal recessive cataract maps to the short arm of chromosome 3

PubMedID: 11519376

Mutations in FYCO1 Cause Autosomal-Recessive Congenital Cataracts

PubMedID: 21636066