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Cataracts 45

OMIM ID:

autosomal recessive

Cataracts 45

Alternate Names

CTRCT45

Defective Genes

SIPA1L3

Clinical Characteristics

Ocular Features

Dense white cataracts have been diagnosed as soon as 2 weeks after birth.

Systemic Features

No dysmorphic features or psychomotor deficits have been found.

Genetics

Inheritance

Homozygous mutations in the SIPA1L3 gene (19q13.1-q13.2) were found in a consanguineous German family in which 2 of 3 female sibs were affected.   The parents were phenotypically normal but heterozygous for the mutation.    

Pedigree

Autosomal recessive

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent.  Carriers with only one mutation, such as the parents, do not have clinical disease.  Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Image
Sample pedigree of autosomal recessive inheritance

In order for autosomal recessive disorders to be expressed, offspring generally must inherit two mutations, one from each carrier parent. Carriers with only one mutation, such as the parents, do not have clinical disease. Note that carrier parents can expect that 1 in 4 children (25%) will inherit both mutations and have the disorder, 2 in 4 children (50%) will be carriers like their parents, while 1 in 4 children (25%) inherit neither mutation.

Treatment & Management

Surgical removal has apparently been successful.

Selected Resources

Web Resources

Publications

Displaying 1 - 2 of 2

Mutations inSIPA1L3cause eye defects through disruption of cell polarity and cytoskeleton organization

PubMedID: 26231217

SIPA1L3 identified by linkage analysis and whole-exome sequencing as a novel gene for autosomal recessive congenital cataract

PubMedID: 25804400